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Task D-004 · Type D — Disease → mechanism

By what mechanism does alpha-galactosidase A deficiency lead to multisystem damage in Fabry disease?

Difficulty
medium
Rarity stratum
high
Evidence type
review consensus
MONDO ID
MONDO:0010526
Curator notes

None material — Gb3/lyso-Gb3 lysosomal accumulation mechanism is consistently described.

Generation outcome

Abstained
No
Abstention correct
Yes
Gold in retrieved
2.00
Generation cost
$0.000469
Claims
3
Supported
3
Contradicted
0
Unverifiable
0

Gold documents (3)

  • Fabry disease cardiomyopathy: A state-of-the-art review.
    pubmed:40840785retrieved ✓source
  • Treatment of Anderson-Fabry Disease.
    pubmed:32183665retrieved ✓source
  • Biomarkers in Anderson-Fabry Disease.
    pubmed:33138098not retrievedsource

Retrieved documents (6)

  • Treatment of Anderson-Fabry Disease.
    pubmed:32183665gold
  • Nucleoside-Modified mRNA Encoding Alpha-Galactosidase A Ameliorates Fabry Disease Phenotypes in Human IPSC-Derived Cardiomyocytes.
    pubmed:42591063
  • Anderson-Fabry disease in heart failure.
    pubmed:29909504
  • Fabry disease cardiomyopathy: A state-of-the-art review.
    pubmed:40840785gold
  • Early Atrial Remodeling Drives Arrhythmia in Fabry Disease.
    pubmed:40557493
  • A composite measurement concept for monitoring cardiac function in Fabry disease.
    pubmed:40722192

Generated claims (3)

supportedconfidence 0.95

Alpha-galactosidase A deficiency leads to accumulation of globotriaosylceramide (Gb3) in lysosomes.

pubmed:40557493pubmed:42591063pubmed:40840785pubmed:29909504
supportedconfidence 0.90

Gb3 accumulation induces pathology via the release of pro-inflammatory cytokines, growth-promoting factors, and oxidative stress.

pubmed:29909504
supportedconfidence 0.90

This results in myocardial extracellular matrix remodelling, left ventricular hypertrophy, vascular dysfunction, interstitial fibrosis, and cardiac arrhythmias.

pubmed:40840785pubmed:40557493pubmed:29909504